Skoči na glavni sadržaj

Sažetak sa skupa

https://doi.org/10.15836/ccar2023.148

Right coronary sinus to pulmonary artery fistula, rare cause of dyspnea: a case report

Anela Subo orcid id orcid.org/0000-0003-3867-2542 ; General Hospital “Prim. Dr Abdulah Nakas”, Sarajevo, Bosnia and Herzegovina
Omer Manov ; University Clinical Hospital Mostar, Mostar, Bosnia and Herzegovina
Azra Sabic ; General Hospital “Prim. Dr Abdulah Nakas”, Sarajevo, Bosnia and Herzegovina
Anita Glavinić ; University Clinical Hospital Mostar, Mostar, Bosnia and Herzegovina
Antonela Krasic Arapovic ; University Clinical Hospital Mostar, Mostar, Bosnia and Herzegovina


Puni tekst: engleski pdf 129 Kb

str. 148-148

preuzimanja: 71

citiraj

Preuzmi JATS datoteku


Sažetak

Ključne riječi

aorto-pulmonary fistula; pulmonary artery; right coronary sinus; pulmonary hypertension; congenital vascular abnormality

Hrčak ID:

301220

URI

https://hrcak.srce.hr/301220

Datum izdavanja:

27.4.2023.

Posjeta: 219 *



Introduction: Aorto-pulmonary fistula is a very rare type of anomalous vascular communication and mainly associated with a risk of heart failure (volume overload, pulmonary hypertension), rupture or dissection, myocardial ischemia, arterial aneurysm or endocarditis. (1-4) The presence of symptoms and evidence of a significant hemodynamic left-right shunt necessitated intervention.

Case report: 73-year-old woman presented to hospital on routine cardiology control exam with the symptom of the progressive dyspnea on exertion over the last 5 years. The patient followed up by the cardiologist a couple of years because of history of dyspnea and fatigue. Except for hypertension, there was no significant other past medical history and all diagnostic tests which were performed to detect etiology of dyspnea was non-diagnostic. 12-led electrocardiogram showed normal sinus rhythm, rate of 72 beats per minute, normal heart axis, and diffuse non-specific T-wave abnormalities. Transthoracic echocardiography demonstrated mild pulmonary regurgitation and pathological, shunt flow, which drained into the left lateral aspect of the main pulmonary trunk. The main differential diagnosis was fistula, patent arterial duct, although other congenital arteriovenous shunts need to be excluded. A high velocity flow shunt was evident in diastole. CT coronary angiography demonstrated a communication between the aortic root and pulmonary artery. It was a well-defined fistula between the right coronary sinus and main pulmonary artery, 1 – 2 cm above the pulmonary valve. The fistula appeared separate to the right coronary ostium and exam ruled out communication with the coronary circulation.

Conclusion: Aorto-pulmonary fistula is very rare and easily misdiagnosed. Pulmonary artery fistulas should be part of the differential diagnosis in a patient symptomatic for dyspnea. Patient with aorto-pulmonary fistula has been referred for surgical or percutaneous correction.

LITERATURE

1 

Gentile F, Castiglione V, De Caterina R. Coronary Artery Anomalies. Circulation. 2021 September 21;144(12):983–96. https://doi.org/10.1161/CIRCULATIONAHA.121.055347 PubMed: http://www.ncbi.nlm.nih.gov/pubmed/34543069

2 

Dungu J, Juli C, Nihoyannopoulos P. Left coronary sinus to pulmonary artery fistula, complicated by pulmonary valve endocarditis. Eur Heart J. 2011 May;32(10):1299. https://doi.org/10.1093/eurheartj/ehq489 PubMed: http://www.ncbi.nlm.nih.gov/pubmed/21193436

3 

Liu X, Zhang L, Qi Z, Fan M, Ge J. The characteristics of coronary-pulmonary artery fistulas and the effectivity of trans-catheter closure: a single center experience. J Thorac Dis. 2019 July;11(7):2808–15. https://doi.org/10.21037/jtd.2019.06.60 PubMed: http://www.ncbi.nlm.nih.gov/pubmed/31463109

4 

Dzelebdzic S, Tawfik S, Collazo L, Shorofsky M, Benheim A, Ansong A, et al. Diagnosis and Management of Fontan Failure Secondary to Aortopulmonary Artery Fistula. Structural Heart Disease. 2019;5(2):38–42. https://doi.org/10.12945/j.jshd.2019.014.18


This display is generated from NISO JATS XML with jats-html.xsl. The XSLT engine is libxslt.